OMKar: Optical Map Based Automated Karyotyping of Genomes to Identify Constitutional Disorders

  • Siavash Raeisi Dehkordi
  • , Zhaoyang Jia
  • , Joey Estabrook
  • , Jen Hauenstein
  • , Neil Miller
  • , Naz Güleray-Lafci
  • , Jürgen Neesen
  • , Alex Hastie
  • , Andy Wing Chun Pang
  • , Paul Dremsek
  • , Vineet Bafna

Research output: Chapter in Book/Report/Conference proceedingConference contributionpeer-review

Abstract

The whole genome karyotype represents the sequence of large chromosomal segments that define an individual’s genotype, encompassing variants such as aneuploidies, balanced, and unbalanced translocations. Karyotype analysis is essential for identifying genetic risk factors, guiding diagnoses, and informing treatment and genetic counseling for constitutional disorders. Optical Genome Mapping (OGM) offers a high-resolution alternative to traditional microscopic karyotyping. We present OMKar, an automated tool that leverages OGM data to generate virtual karyotypes by processing structural variants (SVs) and copy number variants (CNVs) into a breakpoint graph. OMKar employs Integer Linear Programming to ensure chromosomal balance and identifies Eulerian paths to reconstruct chromosomes. In simulation tests, OMKar reconstruction achieved 88% precision and 95% recall for SV concordance and a 95% Jaccard score for CNV concordance. It was further validated on 154 clinical samples from ten different sites, where it successfully reconstructed 144 of the 154 karyotypes. OMKar identified genetic mechanisms for five disorders missed by traditional karyotyping, demonstrating its robustness in detecting constitutional disorders. The tool is publicly available at https://github.com/siavashre/OMKar.

Original languageEnglish
Title of host publicationResearch in Computational Molecular Biology - 29th International Conference, RECOMB 2025, Proceedings
EditorsSriram Sankararaman
PublisherSpringer Science and Business Media Deutschland GmbH
Pages281-284
Number of pages4
ISBN (Print)9783031902512
DOIs
Publication statusPublished - 2025
Externally publishedYes
Event29th International Conference on Research in Computational Molecular Biology, RECOMB 2025 - Seoul, Korea, Republic of
Duration: 26 Apr 202529 Apr 2025

Publication series

NameLecture Notes in Computer Science
Volume15647 LNBI
ISSN (Print)0302-9743
ISSN (Electronic)1611-3349

Conference

Conference29th International Conference on Research in Computational Molecular Biology, RECOMB 2025
Country/TerritoryKorea, Republic of
CitySeoul
Period26/04/2529/04/25

Keywords

  • Constitutional disease
  • Karyotyping
  • Optical Genome Mapping

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